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Thymidine Kinase 2 DeficiencyPhase 2ContinuationNCT03845712

An Open-Label Study of Continuation Treatment With Combination Pyrimidine Nucleosides in Patients With TK2 Deficiency

A Phase 2 study testing doxecitine and doxribtimine in people with Thymidine Kinase 2 Deficiency, run by UCB BIOSCIENCES, Inc. at 8 sites in 3 countries.

Completed

Finished. The study has ended and is not enrolling. Results may be posted on the official record.

Official record
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Trial summary

This is a Phase 2 prospective open-label treatment study of the safety and efficacy of doxecitine and doxribtimine in study participants with thymidine kinase 2 (TK2) deficiency who participated in the retrospective study MT-1621-101 [NCT03701568] or who were receiving nucleos(t)ide treatment and were approved by the… Read more about this study

Who is it for?
Any age
Conditions the study is for
Thymidine Kinase 2 Deficiency
What is being tested?
doxecitine and doxribtimine
Type of treatment
Pill or oral medicine
Could I receive a placebo?
No, everyone receives an active treatment
How many people
47 participants
Where
8 sitesin 3 countries
Study dates
5 Jul 2019to 26 Aug 2026
Phase
Phase 2
Are there results?
None posted in the registry

Key requirements

Who can take part, as listed by the sponsor. Only the study team can confirm whether you are eligible, so take this list to your doctor.

  • Ages Any age
  • All sexes
  • No healthy volunteers
  • Child, Adult, Older adult

Who may be able to join

  • Signed informed consent by the parent(s) or legally authorized representative (LAR) and/or assent by the study participant (when applicable).
  • Confirmed genetic mutation in the TK2 gene.
  • Absence of other genetic disease or polygenic disease.
  • Current treatment with nucleos(t)ides for TK2 deficiency. Study participants who were not previously enrolled in MT-1621-101 [NCT03701568] will require Sponsor approval to ensure that collection of clinical and functional measurements prior to treatment are sufficient to serve as baseline assessments for purposes of evaluating safety and efficacy.
  • Female study participants must not be breastfeeding, have a negative pregnancy test at screening (females ≥10 years old), and have no intention to become pregnant during the course of the study. Female study participants who are of childbearing potential (ie, following menarche until ≥1 year post-menopausal if not anatomically and physiologically incapable of becoming pregnant) must agree and commit to the use of highly effective methods of birth control for the duration of the study and for 30 days after the end of the study. Acceptable methods are defined as those that result, alone or in combination, in a low failure rate (ie, <1% per year) when used consistently and correctly, such as surgical sterilization, an intrauterine device, or hormonal contraception in combination with a barrier method. In certain countries (if permitted by law), women of childbearing potential may instead agree to abide by heterosexual sexual abstinence during the study and for 30 days after the end of the study.
  • Male study participants with sexual partners should use condoms for the duration of the study and for 30 days after the last dose of study drug to prevent passing study drug to the partner in the ejaculate. Male participants should be advised not to donate sperm for 30 days after the last dose of study drug.
  • Willingness to maintain current treatment regimen and current exercise regimen for the duration of the clinical study.
  • Willingness to comply with the study protocol, including but not limited to, all study procedures, study visits, and study drug compliance.

Who cannot join

  • History of liver disease, or liver function test results (ALT, AST, or total bilirubin) ≥2× upper limit of normal without prior Sponsor approval.
  • Other significant medical condition that, in the opinion of the Investigator or Study Sponsor, may confound interpretation of the clinical course of TK2 deficiency.

Trial locations and contacts

8 sites in 3 countries.

8 sites in 3 countries

Spain4 sites
  • Tk0102 3102

    Barcelona

  • Tk0102 3121

    Esplugues de Llobregat

  • Tk0102 3031

    Madrid

  • Tk0102 3101

    Seville

Other trials in Spain

Israel3 sites
  • Tk0102 4038

    Haifa

  • Tk0102 4039

    Holon

  • Tk0102 4037

    Nehariya

Other trials in Israel

United States1 site
  • Tk0102 1005

    New York, New York, 10032

Other trials in United States

About this study

Official title: A Phase 2 Open-Label Study of Continuation Treatment With Combination Pyrimidine Nucleosides in Patients With Thymidine Kinase 2 Deficiency (TK2)

This is a Phase 2 prospective open-label treatment study of the safety and efficacy of doxecitine and doxribtimine in study participants with thymidine kinase 2 (TK2) deficiency who participated in the retrospective study MT-1621-101 [NCT03701568] or who were receiving nucleos(t)ide treatment and were approved by the Sponsor.

Being tested
doxecitine and doxribtimine
Keywords
Thymidine Kinase 2 Deficiency, TK2d, mitochondrial disorder, mitochondrial disease, Mitochondria, deoxycytidine and deoxythymidine, doxecitine and doxribtimine, MT1621, primary mitochondrial myopathy, mitochondrial depletion syndrome, Muscle weakness, Muscle atrophy, Loss of mobility
Medical subject headings
Mitochondrial Diseases, Muscle Weakness, Muscular Atrophy

What participants receive

What participants receive. In a randomised study each person is assigned to one group by chance.

  • doxecitine and doxribtimineDrug

    Also called MT1621, GMP grade dC/dT (deoxycytidine and deoxythymidine)

    Doxecitine and doxribtimine is administered orally in 3 equal doses given approximately 6 to 8 hours apart. Doxecitine and doxribtimine is administered with food.

Study groups in NCT03845712
Study groupRoleWhat they receive
doxecitine and doxribtimineExperimentalThis is an open label study with all participants in a single arm. Study participants will take doxecitine and doxribtimine up to a maximum of 800 mg/kg/day (400 mg/kg/day doxecitine and 400 mg/kg/day doxiribtimine).
Receives: Drug: doxecitine and doxribtimine

What is being measured

The primary outcome is the main question the study is designed to answer.

  1. Incidence of treatment-emergent adverse events (TEAEs)

    An AE is any untoward medical occurrence in a patient or clinical study participant, temporally associated with the use of study medication, whether or not considered related to the study medication.

    Measured: From first administration of study drug until end of safety follow-up (up to approximately 7 years)

  2. Incidence of TEAEs leading to study drug withdrawal

    An AE is any untoward medical occurrence in a patient or clinical study participant, temporally associated with the use of study medication, whether or not considered related to the study medication.

    Measured: From first administration of study drug until end of safety follow-up (up to approximately 7 years)

Secondary outcomes (4)
  1. Clinical Global Impression of Improvement (CGI-I) Response score

    The CGI-I rating scale permits a global evaluation by the clinician of the study participant's improvement over time after study drug has been initiated. Improvement in a study participant's condition is rated on a 7-point scale ranging from 1 (very much improved) to 7 (very much worse) as follows: 1 = very much improved, 2 = much improved, 3 = minimally improved, 4 = no change, 5 = minimally worse, 6 = much worse, and 7 = very much worse.

    Measured: Assessed at end of study (approximately 7 years)

  2. Mean minimum plasma concentration (Cmin) of deoxycytidine (dC) and deoxythymidine (dT) at steady state

    Cmin = Minimum plasma concentration

    Measured: Plasma samples will be collected at Months 1, 3, and 6

  3. Mean maximum plasma concentration (Cmax) of dC and dT at steady state

    Cmax = Maximum plasma concentration

    Measured: Plasma samples will be collected at Months 1, 3, and 6

  4. Mean area under the plasma concentration - time curve from time 0 to 24 hours (AUC0-24) of dC and dT at steady state

    AUC0-24 = Area under the plasma concentration-time curve from 0 to 24 hours

    Measured: Plasma samples will be collected at Months 1, 3, and 6

Timeline

From the start of the study to its completion; the mark is today. Estimated dates are the sponsor’s plan.

  1. First posted19 Feb 2019
  2. Study start5 Jul 2019
  3. Primary completion26 Aug 2026
  4. Study completion26 Aug 2026

Resources

More details

For doctors and researchers: how the study is designed, who runs it, and its registry IDs.

Study design
Study type
Interventional
Phase
Phase 2
Primary purpose
Treatment
Allocation
Not applicable
Intervention model
Single group
Masking
None (open label)
Enrolment
47 participants (actual)
IDs, dates and publications
ClinicalTrials.gov ID
NCT03845712
Sponsor's protocol ID
TK0102
Other IDs
2018-004277-27, U1111-1304-0423, 2023-510427-29, 2023, 2018
Acronym
Continuation
Status last verified
Sep 2026
First submitted
6 Feb 2019
Last updated
8 Sep 2026
Results posted
No
Data monitoring committee
Yes
FDA-regulated drug
Yes
FDA-regulated device
No
Individual data sharing
Yes: Data from this trial may be requested by qualified researchers six months after product approval in the US and/or Europe, or global development is discontinued, and 18 months after trial completion. Investigators may request access to anonymized individual patient-level data and redacted trial documents which may include: analysis-ready datasets, study protocol, annotated case report form, statistical analysis plan, dataset specifications, and clinical study report. Prior to use of the data, proposals need to be approved by an independent review panel at www.Vivli.org and a signed data sharing agreement will need to be executed. All documents are available in English only, for a prespecified time, typically 12 months, on a password protected portal. This plan may change if the risk of re-identifying trial participants is determined to be too high after the trial is completed; in this case and to protect participants, individual patient-level data would not be made available.
Expanded access
Available

Publications

  • Hernandez-Voth A, Sayas Catalan J, Corral Blanco M, Castano Mendez A, Martin MA, De Fuenmayor Fernandez de la Hoz C, Villena Garrido V, Dominguez-Gonzalez C. Deoxynucleoside therapy for respiratory involvement in adult patients with thymidine kinase 2-deficient myopathy. BMJ Open Respir Res. 2020 Nov;7(1):e000774. doi: 10.1136/bmjresp-2020-000774.

    PubMed 33246973

Questions about this trial

What is this clinical trial studying?

A Phase 2 study testing doxecitine and doxribtimine in people with Thymidine Kinase 2 Deficiency, run by UCB BIOSCIENCES, Inc. at 8 sites in 3 countries.

The full registered description is in the About this study section and the official record.

Who may be eligible to take part?

The sponsor lists 8 inclusion and 2 exclusion criteria. Eligibility is decided by the study team after screening, so read the full criteria and contact a listed site.

Is this clinical trial currently recruiting?

The record says: finished, as of the sponsor's last update on 8 Sep 2026. Status can change between updates, so confirm with the study contact before making plans.

Where is the study taking place?

The record lists 8 sites in Spain, Israel, United States. Whether a site is taking part right now should be confirmed with that site. See every site.

What are the possible benefits and risks?

They depend on the study and the treatment, and no study can promise a benefit. The study team explains the known risks during informed consent, before anyone joins; the record itself does not list them.

What does this phase mean?

Phase 2 studies give the treatment to a larger group to see whether it has the intended effect and to keep checking safety.

Not every study follows the same path, and some studies (observational studies, device studies) have no phase.

Are results available for this study?

The study is completed, but results are not available in the source record. That does not mean the treatment did or did not work.

How can a doctor refer a patient or contact the research team?

The record lists no contact. The official record names the sponsor, who can be asked directly. AzTrials does not enrol participants or take referrals.

What does the primary outcome measure?

Incidence of treatment-emergent adverse events (TEAEs) (time frame: From first administration of study drug until end of safety follow-up (up to approximately 7 years)). The study lists 2 primary outcomes in all. It is what the study was designed to measure, not a finding.

Where can I read the original study information?

On the ClinicalTrials.gov record for NCT03845712, which also lists 1 linked publication.

Does a listing mean the treatment is approved or proven to work?

No. A listing means the study is registered. It does not show that the treatment is safe, works, or is approved by a regulator.

How often is this information updated?

AzTrials copies changed records from ClinicalTrials.gov every night and reloads the whole registry every week. The sponsor last updated this record on 8 Sep 2026.

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