Spinal Muscular Atrophy (SMA)NCT04174157
Registry of Patients With a Diagnosis of Spinal Muscular Atrophy (SMA)
An observational study of Spinal Muscular Atrophy (SMA), run by Novartis Pharmaceuticals at 99 sites in 11 countries.
Trial summary
Spinal muscular atrophy (SMA) is a neurogenetic disorder caused by a loss or mutation in the survival motor neuron 1 gene (SMN1) on chromosome 5q13, which leads to reduced SMN protein levels and a selective dysfunction of motor neurons. Read more about this study
- Who is it for?
- Any age
- Conditions the study is for
- Spinal Muscular Atrophy (SMA)
- What is being tested?
- Prospective observational registry and Zolgensma
- How many people
- 700 participants
- Where
- 99 sitesin 11 countries
- Study dates
- 25 Sep 2018to 30 Jun 2038
- How long will I take part?
- 15 Years
- Phase
- Observational
- Are there results?
- Not yet: the study is under way
Key requirements
Who can take part, as listed by the sponsor. Only the study team can confirm whether you are eligible, so take this list to your doctor.
- Ages Any age
- All sexes
- No healthy volunteers
- Child, Adult, Older adult
Study population: The study will enroll at least 500 patients with a genetically confirmed diagnosis of SMA. The registry will attempt to enroll all patients treated with OAV-101 in the registry until the end of 2026.
Who may be able to join
- Patients treated with OAV-101 with a genetically confirmed diagnosis of SMA regardless of the date of diagnosis.
- Appropriate consent/assent has been obtained for participation in the registry
Who cannot join
- Currently enrolled in an interventional clinical trial involving an investigational medicinal product to treat SMA.
- Note: Patients who are participating in a Compassionate Use Program (CUP) for OAV-101 (Zolgensma) such as a Managed Access Program (MAP), an Expanded Access Program (EAP), Single Patient Investigational New Drug (IND) (SPI) or Named Patient Program (NPP) are eligible to enroll in the registry regardless of the date of a genetic or clinical diagnosis of SMA.
Trial locations and contacts
99 sites in 11 countries. Contact the study team or a site near you to ask about taking part.
Novartis Gene Therapies contact
99 sites in 11 countries
United States50 sites, 42 recruiting
- Completed
Akron Children's Hospital
Akron, Ohio, 44308-1062
- Recruiting
Children's Hospital Colorado
Aurora, Colorado, 80045
Margaret Finlay, 720-777-1234, margaret.finlay@childrenscolorado.org
Julie Parsons, MD
- Completed
Child Neurology Consultants of Austin
Austin, Texas, 78731
- Recruiting
University of Virginia Health System
Charlottesville, Virginia, 22908
Chelsea Masterson, 434-297-5737, CDM5FA@hscmail.mcc.virginia.edu
Rebecca Scharf, MD
- Recruiting
Cincinnati Children's Hospital Medical Center
Cincinnati, Ohio, 45229-3026
Emily Hunsaker, 513-636-5511, emily.hunsaker@cchmc.org
Cuixia Tian, MD
- Completed
University Hospitals
Cleveland, Ohio, 44106
- Recruiting
University of Missouri Health System
Columbia, Missouri, 65212
Anne Bonnett, 573-884-6119, bonnetta@health.missouri.edu
Jane Emerson, MD
- Recruiting
Nationwide Children's Hospital
Columbus, Ohio, 43205
Megan Waldrop, 614-722-2231, Megan.WAldrop@nationwidechildrens.org
Megan Waldrop, MD
- Completed
Children's Health
Dallas, Texas, 75207
- Recruiting
Duke Health
Durham, North Carolina, 27705
Karen Cornett, 919-684-1143, k.cornett@duke.edu
Mai Elmallah, MD
- Recruiting
Connecticut Children's Medical Center
Farmington, Connecticut, 06034
Hendriana Nielsen, 860-837-5881, HNielsen@connecticutchildrens.org
James Santanelli, (860) 837-5873, jsantanelli@connecticutchidlrens.org
- Recruiting
Golisano Children's Hospital of Southwest Florida
Fort Myers, Florida, 33908
Britt Stroud, MD, 239-343-5437, britt.stroud@leehealth.org
Molly Arnstrom, (239) 343-5437, Molly.arnstrom@leehealth.org
- Recruiting
Cook Children's
Fort Worth, Texas, 76104
Kayla Blough, 682-319-5312, Kayla.blough@cookchildrens.org
Warren Marks, MD
- Recruiting
Prisma Health
Greenville, South Carolina, 29615
Addie Hunnicutt Hunnicutt, 864-454-5110, ahunnicutt@ghs.org
Addie Hunnicutt, (864) 454-5110, ahunnicutt@ghs.org
- Recruiting
Penn State Hershey
Hershey, Pennsylvania, 17033
Ellen Stoute, 717-531-1260, estoute@pennstatehealth.psu.edu
Ashutosh Kumar, MD, (717) 531-8790, akumar5@pennstatehealth.psu.edu
- Recruiting
Texas Children's Hospital
Houston, Texas, 77030
Felize Singleton, 832-824-1640, felize.singleton@bcm.edu
Timothy Lotze, MD
- Recruiting
Indiana University Health University Hospital (IUHUH)
Indianapolis, Indiana, 46202
Marcia Felker, MD, 317-948-7450, mamccann@iupui.edu
Leanne Dunn, 317-278-7815, lkhernan@iu.edu
- Recruiting
University of Iowa
Iowa City, Iowa, 52242-1009
Chandra Miller, 319-384-9618, Chandra-miller@uiowa.edu
Carrie Stephan, (319) 356-2673, Carrie-stephan@uiowa.edu
- Recruiting
University of Kansas Medical Center
Kansas City, Kansas, 66160
Rebecca Clay, 913-588-1227, rclay@kumc.edu
Jeffrey Statland, MD
- Recruiting
Arkansas Children's Hospital
Little Rock, Arkansas, 72202
Kapil Arya, 501-364-1850, karya@uams.edu
Kapil Arya, MD
- Completed
Loma Linda University Health
Loma Linda, California, 92350
- Recruiting
Children's Hospital of Los Angeles
Los Angeles, California, 90027
Martha Arellano-Garcia, 323-361-5812, margarcia@chla.usc.edu
Claudia Dozal, (323) 361-5825, cdozal@chla.usc.edu
- Recruiting
University of California Los Angeles Health
Los Angeles, California, 90095
Huynh Jennifer, 310-825-3564, JenniferH@mednet.ucla.edu
Perry Shieh, MD, PhD
- Recruiting
University of Louisville
Louisville, Kentucky, 40202
Lauren Evanczyk, 502-588-3650, Lauren.evanczyk@nortonhealthcare.org
Arpita Lakhotia, MD
- Recruiting
Valley Children's Healthcare
Madera, California, 93636
Raymund David, MD, 559-353-6215, RDavid@valleychildrens.org
Raymund David, MD
- Recruiting
Children's Hospital of Orange County
Madera, California, 93638
Amanda Fernandez, MD, 559-353-6215, afernandez@choc.org
Linda Do, (714) 696-2665, Linh.Do@choc.org
- Recruiting
University of Wisconsin
Madison, Wisconsin, 53792
Maggie Chilsen, 608-263-2704, mchilsen@clinicaltrials.wisc.edu
Jennifer Kwon, MD
- Recruiting
Methodist Le Bonheur Healthcare
Memphis, Tennessee, 38103
Farimah Salami, 901-287-4509, Farimah.Salami@lebonheur.org
Elena Caron, MD
- Completed
Nicklaus Children's Hospital
Miami, Florida, 33155
- Recruiting
Children's Hospital of Wisconsin
Milwaukee, Wisconsin, 53226
Rupa Nallamothu, 414-955-0685, rnallamothu@mcw.edu
Rebecca Rehborg, (414) 805-8369, rrehborg@mcw.edu
- Recruiting
University of Minnesota
Minneapolis, Minnesota, 55455
Seth Stafki, MD, 218-298-2747, stafk006@umn.edu
Peter Karachunski, MD
- Recruiting
Atlantic Health System
Morristown, New Jersey, 07960
Darius Adams, MD, 518-262-5120, adamsd@mail.amc.edu
Darius Adams, MD
- Recruiting
Yale-New Haven Health System
New Haven, Connecticut, 06510
Catherine Tsao, 203-785-4390, catherine.tsao@yale.edu
Cristian Ionita, MD
- Recruiting
Children's Hospital of The King's Daughters
Norfolk, Virginia, 23507
Cassandra Todd, 757-846-1969, Cassandra.Todd@chkd.org
Crystal Proud, MD
- Completed
Oklahoma University Medical Center
Oklahoma City, Oklahoma, 73104
- Completed
Adventist Health System - Florida
Orlando, Florida, 32803
- Recruiting
Jackson South Medical Center
Palmetto Bay, Florida, 33157
Paula Schleifer, MD, 305-279-2226, pschleifer@fcneurology.net
Paula Schleifer, MD
- Recruiting
Phoenix Children's Hospital
Phoenix, Arizona, 85016
Alison Lane, 602-933-0885, alane@phoenixchildrens.com
Saunder Bernes, MD
- Recruiting
University of Pittsburgh Medical Center
Pittsburgh, Pennsylvania, 15224
Emma Sekscinski, 302-393-6102, ecs112@pitt.edu
Hoda Abdel-Hamid, MD
- Recruiting
Oregon Health and Science University
Portland, Oregon, 97239-3098
Bryn McCarthy, 503-418-8297, McCarbry@ohsu.edu
Erika Finanger, MD
- Recruiting
Virginia Commonwealth University Health System
Richmond, Virginia, 23298
Ana Rosa Rezeq, 804-828-1445, Anarosa.rezeq@vcuhealth.org
Amy Harper, MD
- Recruiting
University of Rochester Medical Center
Rochester, New York, 14642
Bohoon Lee, 585-275-2776, Bohoon_Lee@URMC.Rochester.edu
Kim Hart Kim_, Hart@URMC.Rochester.edu
- Recruiting
University of California Davis Health System
Sacramento, California, 95817
Rachel (Ja Yoon) Baek, 916-734-2439, jrbaek@ucdavis.edu
Nanette Joyce, DO
- Recruiting
University of Utah
Salt Lake City, Utah, 84113
Sarah Moldt, 801-585-9399, sarah.moldt@hsc.utah.edu
Russell Butterfield, MD, PhD
- Recruiting
CHRISTUS Health
San Antonio, Texas, 78207
Melissa Svoboda, MD, 210-704-4715, melissa.svoboda@bcm.edu
Melissa Svoboda, MD
- Recruiting
Rady Children's Hospital San Diego
San Diego, California, 92123
Chamindra Konersman, MD, 858-966-5819, ckonersman@health.ucsd.edu
Napat Intarachumnum, 858-576-1700, nintarachumnum@health.ucsd.edu
- Recruiting
Seattle Children's
Seattle, Washington, 98105
Marissa Robertson, 206-987-5457, Marissa.Robertson@seattlechildrens.org
Seth Perlman, MD
- Recruiting
Washington University School of Medicine in St. Louis
St Louis, Missouri, 63110
Natalie Goedeker, 314-362-4919, ngoedeker@wustl.edu
Craig Zaidman, MD
- Recruiting
The State University of New York
Stony Brook, New York, 11794
Christine Pol, 631-444-9083, Christiana.Pol@stonybrookmedicine.edu
Simona Treidler, MD
- Recruiting
MultiCare Health System
Tacoma, Washington, 98405
Beky Stone, 971-319-0237, Becky.Stone@multicare.org
Anisha Schwarz, MD
Japan19 sites
- Active, not recruiting
Chiba children's Hospital
Chiba, Chiba, 266-0007
- Active, not recruiting
Fukui Prefectural Hospital
Fukui, 910-8526
- Active, not recruiting
Gifu Prefectural General Medical Center
Gifu, Gifu, 500-8717
- Active, not recruiting
Hamamatsu University School of Medicine, University Hospital
Hamamatsu, Shizuoka, 431-3192
- Active, not recruiting
Obihiro Kosei Hospital
Hokkaido, Obihiro-shi, 080-0024
- Active, not recruiting
Nikko Memorial Hospital
Hokkaido, 051-0005
- Active, not recruiting
Kagawa University Hospital
Kita-gun, Kagawa-ken, 761-0793
- Active, not recruiting
Kumamoto University Hospital
Kumamoto, Kumamoto, 860-8556
- Active, not recruiting
Kurume University Hospital
Kurume-shi, Fukuoka, 830-0011
- Active, not recruiting
Shiga Medical Center for Children
Moriyama-shi, Shiga, 524-0022
- Active, not recruiting
Aichi Medical University Hospital
Nagakute-shi, Aichi-ken, 480-1195
- Active, not recruiting
Dokkyo Medical University Saitama Medical Center
Saitama, 343-0845
- Active, not recruiting
Sapporo Medical University Hospital
Sapporo, Hokkaido, 060-8543
- Active, not recruiting
Miyagi Children's Hospital
Sendai, Miyagi, 989-3126
- Active, not recruiting
Jichi Medical University Hospital
Shimotsuke-shi, Tochigi, 329-0498
- Active, not recruiting
Tokyo Medical University Hospital
Shinjuku-ku, Tokyo, 160-0023
- Active, not recruiting
Center Hospital of the National Center for Global Health and Medicine
Shinjuku-ku, Tokyo, 162-8655
- Active, not recruiting
Fujita Health University Hospital
Toyoake-shi, Aichi-ken, 470-1192
- Active, not recruiting
Kanagawa Children's Medical Center
Yokohama, Kanagawa, 232-8555
South Korea7 sites, 7 recruiting
- Recruiting
Kyungpook National University Hospital
Daegu, 41944
Jeong Jin Yun, SC, +82-10-7942-7673, sylyu01@naver.com
Yunjeong Lee, MD
- Recruiting
Seoul National University Bundang Hospital
Seongnam-si, 13620
Anna Cho, MD, +82-31-787-7301, annacho77@snu.ac.kr
Anna Cho, MD
- Recruiting
Seoul National University Children's Hospital
Seoul, 03080
Miae Kim, SC, +82-2-6072-5185, sellykma@snuh.org
MD
- Recruiting
Severance Hospital
Seoul, 03722
Hoonchul Kang, MD, 02-2228-2050, HIPO0207@yuhs.ac
Hoonchul Kang, MD
- Recruiting
Samsung Medical Centre
Seoul, 06351
Min Jeong Kim, SC, +82-2-2148-7606, tgkimmj@naver.com
Jiwon Lee
- Recruiting
Pusan National University Yangsan Hospital
Yangsan, 50612
Yunjin Lee, MD, +82-55-360-2180, jinnyeye@hanmail.net
Yunjin Lee, MD
- Recruiting
Yongin Severance Hospital
Yongin-si, 16995
Lae-song Noh, SC, +82-10-4061-2483, YI771998@yuhs.ac
Haneul Lee
Portugal5 sites, 5 recruiting
- Recruiting
CHUC - Hospital Pediatrico
Coimbra, 300-6020
Joana Ribeiro, MD, (+351) 239 800 100, 10675@chuc.min-saude.pt
Joana Ribeiro, MD
- Recruiting
Centro Hospitalar Universitaria de Lisboa Central, EPE
Lisbon, 1169-045
Jose Pedro Vieira, MD, (+351) 213 126 944, Jose.vieira@chlc.min-suade.pt
Jose Pedro Vieira, MD
- Recruiting
Centro Hospitalar Universitario Lisboa Norte, EPE
Lisbon, 1649-035
Teresa Moreno, MD, (+351) 915 668 130, ped.ensaioscaml@gmail.com
Joana Coelho, MD, (+351) 965 560 339, joanamalveirocoelho@gmail.com
- Recruiting
Centro Hospitalar Universitario de Porto, EPE
Porto, 4050-371
Cristina Garrido, MD, (+351) 222 077 500, cgarridopt@gmail.com
Cristina Garrido, MD
- Recruiting
Centro Hospitalar Universitario de Sao Joao, EPE
Porto, 4200-319
Raquel Carvalho Sousa, MD, (+351) 225 512 100, Rccarvalhosousa@gmail.com
Raquel Carvalho Sousa
Taiwan5 sites, 5 recruiting
- Recruiting
Kaohsiung Medical University Chung-Ho Memorial Hospital
Kaohsiung City, 80756
Yuh-Jyh Jong, MD, +886-7-312-1101 ext. 6507, yjjong@gap.kmu.edu.tw
Yuh-Jyh Jong, MD
- Recruiting
China Medical University Hospital
Taichung, 404327
I-Ching Chou, MD, +886- 4-22052121, 004009@tool.caaumed.org.tw
+886- 4-22052121 ext. 4641, 004009@tool.caaumed.org.tw
- Recruiting
National Taiwan University Hospital
Taipei, 100229
Yin-Hsiu CHIEN, MD, +886-2-23123456 #271937, chienyh@ntu.edu.tw
Yin-Hsiu CHIEN, MD
- Recruiting
Taipei Veterans General Hospital
Taipei, 11217
Dau-Ming NIU, MD, +886-2-28712121 #8486, dmniu1111@yahoo.com.tw
Dau-Ming NIU
- Recruiting
Chang Gung Memorial Hospital Linkou Branch
Taoyuan, 333
I-Jun CHOU, MD, +886-3-328-1200 #7865, ijun@adm.cgmh.org.tw
I-Jun CHOU, MD
Greece4 sites, 4 recruiting
- Recruiting
University General Hospital Attikon
Chaïdári, Athens, 124 62
Argyrios Dinopoulos, MD, +30 210 583 1000, argidino@yahoo.com
Argyrios Dinopoulos, MD
- Recruiting
Penteli Children's Hospital
Pentéli, Attikis, 152 36
Chrysanthi Tsimakidi, +30 213 205 2200, Chrysanthit@hotmail.com
Chrysanthi Tsimakidi
- Recruiting
St. Sophia Children's Hospital
Thessaloniki, 115 27
Maria Roser-Pons, MD, +30 213 201 3000, roserpons@med.uoa.gr
Maria Roser-Pons, MD, MD
- Recruiting
General Hospital of Thessaloniki Ippokrateio
Thessaloniki, 546 42
Dimitrios Zafeiriou, MD, +30 2310 99 29 63, dizafeir@auth.gr
Dimitrios Zafeiriou, MD
Israel4 sites, 4 recruiting
- Recruiting
Soroka Medical Centre
Beersheba, 85025
Iris Noyman, MD, 972-86245911, IRISN@clalit.org.il
Iris Noyman, MD
- Recruiting
Wolfson Medical Center
Holon, 5822012
Mira Ginsberg, MD, 972-3-5028936, miraginsberg@gmail.com
Mira Ginsberg, MD
- Recruiting
Tel-Aviv Sourasky Medical Center
Holon, 582201
Aviva Fattal, MD, 972-3-6974115, afatal@post.tau.ac.il
Aviva Fattal, MD
- Recruiting
Schneider- Children's Medical Center
Petah Tikva, 4920235
Sharon Aharoni, MD, 972-3-9253398, Sharonah@clalit.org.il
Sharon Aharoni, MD
Romania2 sites, 2 recruiting
- Recruiting
Centrul de Recuperare pentru Copii dr. Nicolae Robanescu
Bucharest, 041408
Madalina Cristina Leanca, MD, (+40) 726 274 907, mada332@yahoo.com
Madalina Cristina Leanca
- Recruiting
Spitalul Clinic de Psihiatrie
Bucharest, 041914
Loana Minciu, MD, (+40) 722 548 137, Iminciu@yahoo.com
Loana Minciu
Ireland1 site, 1 recruiting
- Recruiting
Children's University Hospital-UCD School of Medicine Scoil an Leighis
Dublin, 1 D01 XD99
Declan O Rourke, MD, +353 1 8784722, declan.orourke@cuh.ie
Poland1 site, 1 recruiting
- Recruiting
Uniwersytecki Szpital Dzieciec
Lublin, 20-093
Magdalena Chroscinska-Krawczyk, MD, (+48) 669 487 491, magdalenachk@wp.pl
Magdalena Chroscinska-Krawczyk, MD
Russia1 site, 1 recruiting
- Recruiting
Almazov National Medical Research Centre
Saint Petersburg, 197341
Natalia Petrova, MD, +79110090808, natalja5@yandex.ru
Natalia Petrova, md
About this study
Official title: A Prospective, Long-Term Registry of Patients With a Diagnosis of Spinal Muscular Atrophy (SMA)
Spinal muscular atrophy (SMA) is a neurogenetic disorder caused by a loss or mutation in the survival motor neuron 1 gene (SMN1) on chromosome 5q13, which leads to reduced SMN protein levels and a selective dysfunction of motor neurons. SMA is an autosomal recessive, early childhood disease with an incidence of 1:10,000 live births. SMA is the leading cause of infant mortality due to genetic diseases.
The purpose of this registry is to assess the long term outcomes of patients with SMA in the context of advances in treatment options and also to characterize and assess long-term safety and effectiveness of OAV-101.
Read the detailed description
This is a prospective, multi center, multinational, non-interventional observational study. All patients will be managed according to the clinical site's normal clinical practice, i.e., the diagnostic and clinical treatment/practice process that a clinician chooses according to their clinical judgement for an SMA patient. Clinical care will not be driven by the protocol. No additional visits or investigations will be performed beyond normal clinical practice. Patients will be followed for 15 years from enrolment or until death, whichever is sooner.
- Conditions
- Spinal Muscular Atrophy (SMA)
- Being tested
- Prospective observational registry, Zolgensma
- Medical subject headings
- Muscular Atrophy, Spinal
What participants receive
What participants receive. In a randomised study each person is assigned to one group by chance.
Prospective observational registryOther
This prospective observational registry will assess long-term outcomes of patients with a diagnosis of SMA.
ZolgensmaDrug
Zolgensma will be given to patients as per normal clinical practice and clinical care will not be mandated by the protocol. As such, the decision to prescribe Zolgensma is separate from the decision to include the patient in this study
| Study group | Role | What they receive |
|---|---|---|
| Prospective observational registry | This is a prospective, multi center, multinational, non-interventional observational registry. Receives: Other: Prospective observational registry; Drug: Zolgensma |
What is being measured
The primary outcome is the main question the study is designed to answer.
Change in probability of survival of all patients with SMA using Kaplan Meier method to estimate
Measured: Based on information collected at Baseline and every 6 months through 2 years of follow-up, then annually through 15 years of follow up.
Change from baseline Children's Hospital of Philadelphia Infant Test of Neuromuscular Disorders (CHOP-INTEND) in infants with pre-symptomatic or type I SMA
CHOP INTEND score ranges from 0 to 64 with higher scores indicating higher motor function
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline Hammersmith Infant Neurological Examination (HINE) in infants with pre-symptomatic, type I or type II SMA
HINE score range from 0 to 26 with higher scores indicating more development.
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in Hammersmith Functional Motor Scale Expanded (HFMSE) for patients with type II and III SMA
HFMSE score range from 0 to 66 with the higher scores indicating more development.
Measured: Baseline and every 6months through 2 years of follow up, then annually through 15 years of follow up
Incidence of treatment emergent adverse events
Measured: Through 15 years of follow up
Incidence of treatment emergent serious adverse events
Measured: Through 15 years of follow up
Incidence of treatment emergent adverse events related to therapy
Measured: Through 15 years of follow up
Incidence of treatment emergent thrombocytopenia, hepatotoxicity and cardiac adverse events
Measured: Through 15 years of follow up
Secondary outcomes (7)
Change from baseline in rates of hospitalization
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in Zarit Burden Interview
Zarit Burden Total Score ranges from 0 to 88. A higher score correlates with higher level of burden.
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in PedsQL Patient interview
PedsQL Total Scale Score is average of all items and ranges from 0 to 100. A higher score correlates with better Health-Related Quality of Life
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in PedsQL Parent interview
PedsQL Total Scale Score is average of all items and ranges from 0 to 100. A higher score correlates with better Health-Related Quality of Life
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in percent of patients requiring ventilator support (BiPAP, Endotracheal tube)
Measured: : Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in in percent of patients requiring nutritional support (Gastrostomy Tube, Gastrojejunal tube (GT) with Nissen fundoplication, GT without Nissen fundoplication, Nasogastrictube, Nasojejunaltube or Percutaneous endoscopic gastrostomy)
Measured: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in in percent of patients requiring mobility device support (Ankle-Foot Orthoses, Supramalleolar Orthosis, Orthotic/shoe inserts, Knee immobilizers, Knee-Ankle-Foot Orthoses , Hand splints, Spinal bracing)
Measured: : Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Timeline
From the start of the study to its completion; the mark is today. Estimated dates are the sponsor’s plan.
- First posted22 Nov 2019
- Study start25 Sep 2018
- Primary completion30 Jun 2038 (estimated)
- Study completion30 Jun 2038 (estimated)
Resources
- Official record on ClinicalTrials.govThe registry entry this page is built from, with its full change history.
- Publications (3)Papers the sponsor has linked to this study.
- Other trials for Spinal Muscular Atrophy (SMA)Studies of the same condition, open and under way.
- More trials run by Novartis PharmaceuticalsThe sponsor's other registered studies.
- What the trial phases meanHow a treatment moves from first tests in people to approval.
More details
For doctors and researchers: how the study is designed, who runs it, and its registry IDs.
Study design
- Study type
- Observational
- Observational model
- Ecologic or community
- Time perspective
- Prospective
- Enrolment
- 700 participants (estimated)
- Target duration
- 15 Years
Sponsor and investigators
- Lead sponsor
- Novartis Pharmaceuticals
- Sponsor type
- Industry (pharma, biotech, devices)
- Responsible party
- Sponsor
- Investigators
- Novartis Pharmaceuticals, Study director, Novartis Pharmaceuticals
IDs, dates and publications
- ClinicalTrials.gov ID
- NCT04174157
- Sponsor's protocol ID
- COAV101A12001
- Status last verified
- Jan 2025
- First submitted
- 12 Sep 2019
- Last updated
- 31 Jan 2025
- Results posted
- No
- FDA-regulated drug
- Yes
- FDA-regulated device
- No
- Individual data sharing
- Undecided: Authorship of planned manuscripts for submission to medical journals shall be determined in accordance with the International Committee of Medical Journal Editors (ICMJE) Uniform Requirements for Manuscripts Submitted to Biomedical Journals (www.icmje.org). The physician agrees that if the physician is part of a multi-center registry, the physician shall coordinate in advance any intended disclosure of the results of the registry with Novartis Gene Therapies to ensure that the results of individual physicians are not published or presented before those of the multi-center registry, unless otherwise agreed to in writing by Novartis Gene Therapies.
- Expanded access
- Available
Publications
Sugarman EA, Nagan N, Zhu H, Akmaev VR, Zhou Z, Rohlfs EM, Flynn K, Hendrickson BC, Scholl T, Sirko-Osadsa DA, Allitto BA. Pan-ethnic carrier screening and prenatal diagnosis for spinal muscular atrophy: clinical laboratory analysis of >72,400 specimens. Eur J Hum Genet. 2012 Jan;20(1):27-32. doi: 10.1038/ejhg.2011.134. Epub 2011 Aug 3.
PubMed 21811307Saito K, Benguerba K, Tsuchida K, Yazawa K, Tsumiyama I, Kayama H, Reyna SP, Khan F, Finkel RS. Onasemnogene Abeparvovec in Patients With SMA: Interim Results of the RESTORE Registry in Japan. Ann Clin Transl Neurol. 2026 Jun 9:10.1002/acn3.70437. doi: 10.1002/acn3.70437. Online ahead of print.
PubMed 42265796Erbas Y, Servais L, Shieh PB, Goedeker NL, Waldrop MA, Bo R, Raju D, Benguerba K, Reyna SP, Wolff D, Finkel RS. Trach and treat: Safety and motor outcomes following onasemnogene abeparvovec in patients with spinal muscular atrophy and tracheostomies in the RESTORE registry. J Neuromuscul Dis. 2026 Jul;13(4):788-794. doi: 10.1177/22143602251395173. Epub 2025 Nov 11.
PubMed 41217888
Study at a glance
From the registry record, last updated by the sponsor on 31 Jan 2025. Recruitment status is as the sponsor reported it: confirm with the study team.
- Official title
- A Prospective, Long-Term Registry of Patients With a Diagnosis of Spinal Muscular Atrophy (SMA)
- ClinicalTrials.gov ID
- NCT04174157
- Acronym / sponsor ID
- COAV101A12001
- Conditions
- Spinal Muscular Atrophy (SMA)
- Study type
- Observational
- Recruitment status
- Recruiting
- Enrolment
- 700 participants (estimated)
- Lead sponsor
- Novartis PharmaceuticalsIndustry (pharma, biotech, devices)
- Study start
- 25 Sep 2018 (actual)
- Primary completion
- 30 Jun 2038 (estimated)
- Study completion
- 30 Jun 2038 (estimated)
- First posted
- 22 Nov 2019 (actual)
- Results
- Not posted in the source record
Clinical summary
The research question as the sponsor registered it. This describes what the study plans to test, not what it found.
Spinal muscular atrophy (SMA) is a neurogenetic disorder caused by a loss or mutation in the survival motor neuron 1 gene (SMN1) on chromosome 5q13, which leads to reduced SMN protein levels and a selective dysfunction of motor neurons. SMA is an autosomal recessive, early childhood disease with an incidence of 1:10,000 live births. SMA is the leading cause of infant mortality due to genetic diseases.
The purpose of this registry is to assess the long term outcomes of patients with SMA in the context of advances in treatment options and also to characterize and assess long-term safety and effectiveness of OAV-101.
Detailed description
This is a prospective, multi center, multinational, non-interventional observational study. All patients will be managed according to the clinical site's normal clinical practice, i.e., the diagnostic and clinical treatment/practice process that a clinician chooses according to their clinical judgement for an SMA patient. Clinical care will not be driven by the protocol. No additional visits or investigations will be performed beyond normal clinical practice. Patients will be followed for 15 years from enrolment or until death, whichever is sooner.
Study design
- Observational model
- Ecologic or community
- Time perspective
- Prospective
- Target follow-up
- 15 Years
- Number of arms
- 1
| Arm | Type | Receives |
|---|---|---|
| Prospective observational registry | – | Other: Prospective observational registry, Drug: ZolgensmaThis is a prospective, multi center, multinational, non-interventional observational registry. |
Who may qualify
- Sex
- All
- Healthy volunteers
- Not accepted
- Age groups
- Child, Adult, Older adult
- Study population
- The study will enroll at least 500 patients with a genetically confirmed diagnosis of SMA. The registry will attempt to enroll all patients treated with OAV-101 in the registry until the end of 2026.
Key inclusion criteria (2 listed)
- Patients treated with OAV-101 with a genetically confirmed diagnosis of SMA regardless of the date of diagnosis.
- Appropriate consent/assent has been obtained for participation in the registry
Key exclusion criteria (2 listed)
- Currently enrolled in an interventional clinical trial involving an investigational medicinal product to treat SMA.
- Note: Patients who are participating in a Compassionate Use Program (CUP) for OAV-101 (Zolgensma) such as a Managed Access Program (MAP), an Expanded Access Program (EAP), Single Patient Investigational New Drug (IND) (SPI) or Named Patient Program (NPP) are eligible to enroll in the registry regardless of the date of a genetic or clinical diagnosis of SMA.
Eligibility is decided by the study team after screening; this overview does not establish that a patient qualifies. Full inclusion and exclusion criteria.
Interventions
| Intervention | Type | Arms |
|---|---|---|
| Prospective observational registryThis prospective observational registry will assess long-term outcomes of patients with a diagnosis of SMA. | Other | Prospective observational registry |
| ZolgensmaZolgensma will be given to patients as per normal clinical practice and clinical care will not be mandated by the protocol. As such, the decision to prescribe Zolgensma is separate from the decision to include the patient in this study | Drug | Prospective observational registry |
Primary outcome
Change in probability of survival of all patients with SMA using Kaplan Meier method to estimate
Time frame: Based on information collected at Baseline and every 6 months through 2 years of follow-up, then annually through 15 years of follow up.
Change from baseline Children's Hospital of Philadelphia Infant Test of Neuromuscular Disorders (CHOP-INTEND) in infants with pre-symptomatic or type I SMA
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
CHOP INTEND score ranges from 0 to 64 with higher scores indicating higher motor function
Change from baseline Hammersmith Infant Neurological Examination (HINE) in infants with pre-symptomatic, type I or type II SMA
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
HINE score range from 0 to 26 with higher scores indicating more development.
Change from baseline in Hammersmith Functional Motor Scale Expanded (HFMSE) for patients with type II and III SMA
Time frame: Baseline and every 6months through 2 years of follow up, then annually through 15 years of follow up
HFMSE score range from 0 to 66 with the higher scores indicating more development.
Incidence of treatment emergent adverse events
Time frame: Through 15 years of follow up
Incidence of treatment emergent serious adverse events
Time frame: Through 15 years of follow up
Incidence of treatment emergent adverse events related to therapy
Time frame: Through 15 years of follow up
Incidence of treatment emergent thrombocytopenia, hepatotoxicity and cardiac adverse events
Time frame: Through 15 years of follow up
7 secondary outcomes
Change from baseline in rates of hospitalization
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in Zarit Burden Interview
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in PedsQL Patient interview
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in PedsQL Parent interview
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in percent of patients requiring ventilator support (BiPAP, Endotracheal tube)
Time frame: : Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in in percent of patients requiring nutritional support (Gastrostomy Tube, Gastrojejunal tube (GT) with Nissen fundoplication, GT without Nissen fundoplication, Nasogastrictube, Nasojejunaltube or Percutaneous endoscopic gastrostomy)
Time frame: Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Change from baseline in in percent of patients requiring mobility device support (Ankle-Foot Orthoses, Supramalleolar Orthosis, Orthotic/shoe inserts, Knee immobilizers, Knee-Ankle-Foot Orthoses , Hand splints, Spinal bracing)
Time frame: : Baseline and every 6 months through 2 years of follow up, then annually through 15 years of follow up
Results and safety
This study is still under way. Results are not available in the source record yet.
Research links
- Official record on ClinicalTrials.govLast updated by the sponsor 31 Jan 2025.
- Background: PubMed 21811307Sugarman EA, Nagan N, Zhu H, Akmaev VR, Zhou Z, Rohlfs EM, Flynn K, Hendrickson BC, Scholl T, Sirko-Osadsa DA, Allitto BA. Pan-ethnic carrier screening and prenatal diagnosis for spinal muscular atrophy: clinical laboratory analysis of >72,400 specimens. Eur J Hum Genet. 2012 Jan;20(1):27-32. doi: 10.1038/ejhg.2011.134. Epub 2011 Aug 3.
- Derived from this study: PubMed 42265796Saito K, Benguerba K, Tsuchida K, Yazawa K, Tsumiyama I, Kayama H, Reyna SP, Khan F, Finkel RS. Onasemnogene Abeparvovec in Patients With SMA: Interim Results of the RESTORE Registry in Japan. Ann Clin Transl Neurol. 2026 Jun 9:10.1002/acn3.70437. doi: 10.1002/acn3.70437. Online ahead of print.
- Derived from this study: PubMed 41217888Erbas Y, Servais L, Shieh PB, Goedeker NL, Waldrop MA, Bo R, Raju D, Benguerba K, Reyna SP, Wolff D, Finkel RS. Trach and treat: Safety and motor outcomes following onasemnogene abeparvovec in patients with spinal muscular atrophy and tracheostomies in the RESTORE registry. J Neuromuscul Dis. 2026 Jul;13(4):788-794. doi: 10.1177/22143602251395173. Epub 2025 Nov 11.
- Individual participant dataSharing planned: Undecided. Authorship of planned manuscripts for submission to medical journals shall be determined in accordance with the International Committee of Medical Journal Editors (ICMJE) Uniform Requirements for Manuscripts Submitted to Biomedical Journals (www.icmje.org). The physician agrees that if the physician is part of a multi-center registry, the physician shall coordinate in advance any intended disclosure of the results of the registry with Novartis Gene Therapies to ensure that the results of individual physicians are not published or presented before those of the multi-center registry, unless otherwise agreed to in writing by Novartis Gene Therapies.
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Referral and contact
AzTrials does not enrol participants or take referrals. Contact the study team or a site listed below; they decide who can take part.
Novartis Gene Therapies contact
Novartis Pharmaceuticals study director
Novartis Pharmaceuticals
99 sites in 11 countries: see every site and its status.
Questions about this trial
What is this clinical trial studying?
An observational study of Spinal Muscular Atrophy (SMA), run by Novartis Pharmaceuticals at 99 sites in 11 countries.
The full registered description is in the About this study section and the official record.
Who may be eligible to take part?
The sponsor lists 2 inclusion and 2 exclusion criteria. Eligibility is decided by the study team after screening, so read the full criteria and contact a listed site.
Is this clinical trial currently recruiting?
The record says: looking for participants now, as of the sponsor's last update on 31 Jan 2025. Status can change between updates, so confirm with the study contact before making plans.
Where is the study taking place?
The record lists 99 sites in United States, Japan, South Korea, Portugal, Taiwan and 6 more countries. Whether a site is taking part right now should be confirmed with that site. See every site.
What are the possible benefits and risks?
They depend on the study and the treatment, and no study can promise a benefit. The study team explains the known risks during informed consent, before anyone joins; the record itself does not list them.
Are results available for this study?
This study is still under way. Results are not available in the source record yet.
How can a doctor refer a patient or contact the research team?
Contact Novartis Gene Therapies (1-888-669-6682, novartis.email@novartis.com), or a site near the patient. AzTrials does not enrol participants or take referrals.
What does the primary outcome measure?
Change in probability of survival of all patients with SMA using Kaplan Meier method to estimate (time frame: Based on information collected at Baseline and every 6 months through 2 years of follow-up, then annually through 15 years of follow up.). The study lists 8 primary outcomes in all. It is what the study was designed to measure, not a finding.
Where can I read the original study information?
On the ClinicalTrials.gov record for NCT04174157, which also lists 3 linked publications.
Does a listing mean the treatment is approved or proven to work?
No. A listing means the study is registered. It does not show that the treatment is safe, works, or is approved by a regulator.
How often is this information updated?
AzTrials copies changed records from ClinicalTrials.gov every night and reloads the whole registry every week. The sponsor last updated this record on 31 Jan 2025.