Alport Syndrome, X-LinkedPhase 2CHXLASNCT04937907
Study of Hydroxychloroquine in Patients With X-linked Alport Syndrome in China (CHXLAS)
A Phase 2 study testing Hydroxychloroquine Sulfate 100 milligram (mg) Tab and Benazepril hydrochloride 10 milligram (mg) Tab in people with Alport Syndrome, X-Linked, run by Shanghai Children's Hospital at 1 site in China.
Trial summary
This Phase 2 randomized controlled trial will study the safety, tolerability, and efficacy of Hydroxychloroquine in qualified patients with Alport syndrome. The trial will be open-label, randomized, controlled and will enroll up to 50 patients. Read more about this study
- Who is it for?
- Ages 3 to 18 years
- Conditions the study is for
- Alport Syndrome, X-Linked
- What is being tested?
- Hydroxychloroquine Sulfate 100 milligram (mg) Tab and Benazepril hydrochloride 10 milligram (mg) Tab
- Type of treatment
- Pill or oral medicine
- Could I receive a placebo?
- Yes, some participants may receive a placebo
- How many people
- 50 participants
- Where
- 1 siteChina
- Study dates
- 8 Sep 2021to 31 Dec 2024
- Phase
- Phase 2
- Are there results?
- None posted in the registry
Key requirements
Who can take part, as listed by the sponsor. Only the study team can confirm whether you are eligible, so take this list to your doctor.
- Ages 3 to 18 years
- All sexes
- No healthy volunteers
- Child, Adult
Who may be able to join
- Male or female;
- Age 3-18 years old;
- Diagnosis of Alport syndrome by genetic testing (documented mutation in a gene associated with Alport syndrome, including COL4A3, COL4A4, or COL4A5) or histologic assessment using electron microscopy;
- Screening eGFR ≥ 90 mL/min/1.73 m2;
- ACE inhibitor and/or ARB, the dosing regimen should be stable for at least 4 weeks prior to screening;
- No antirheumatic drugs such as hydroxychloroquine have been used;
- Willing and able to comply with scheduled visits, treatment plan, laboratory tests, and other study procedures;
Who cannot join
- Causes of chronic kidney disease aside from Alport syndrome (including but not limited to other heritable disorders leading to chronic kidney disease, diabetic nephropathy, hypertensive nephropathy, lupus nephritis, IgA nephropathy);
- Prior exposure to hydroxychloroquine;
- Ongoing chronic hemodialysis or peritoneal dialysis therapy;
- Renal transplant recipient;
- Any clinically significant illness within 4 weeks before screening or surgical or medical condition (other than Alport syndrome) that could interfere with the subject's study compliance; confound the study results; impact subject safety; or significantly alter the absorption, distribution, metabolism, or excretion of drugs;
- Participation in other interventional clinical studies;
- Known hypersensitivity to any component of the study drug.
Trial locations and contacts
1 site in 1 country.
China1 site
Shanghai Children's Hospital
Shanghai, Shanghai Municipality, 200062
About this study
Official title: Efficacy and Safety of Hydroxychloroquine in Patients With X-linked Alport Syndrome in China (CHXLAS)
This Phase 2 randomized controlled trial will study the safety, tolerability, and efficacy of Hydroxychloroquine in qualified patients with Alport syndrome. The trial will be open-label, randomized, controlled and will enroll up to 50 patients.
Read the detailed description
This Phase 2 randomized controlled trial will study the safety, tolerability, and efficacy of Hydroxychloroquine in qualified patients with Alport syndrome. The trial will be open-label, randomized, controlled and will enroll up to 50 patients.
Patients in the Phase 2 cohort will be randomized 1:1 to either Hydroxychloroquine Cohort or Comparator Cohort.
All patients in the study will follow the same visit and assessment schedule. Following randomization on Day 1, patients will be scheduled to be assessed during treatment at Weeks 4, 12, and 24. Patients will not receive study drug during a 24-week withdrawal period between Weeks 25 and 48. Patients will also be scheduled to be assessed at an in person follow up visit at Week 36, and 48.
- Conditions
- Alport Syndrome, X-Linked
- Being tested
- Hydroxychloroquine Sulfate 100 milligram (mg) Tab, Benazepril hydrochloride 10 milligram (mg) Tab
- Keywords
- Alport Syndrome, Hydroxychloroquine, Treatment
- Medical subject headings
- Nephritis, Hereditary
What participants receive
What participants receive. In a randomised study each person is assigned to one group by chance.
Hydroxychloroquine Sulfate 100 milligram (mg) TabDrug
Also called HCQ
Patients administered HCQ by oral at a dose of 6.5mg per kilogram twice a day at least 6 months.
Benazepril hydrochloride 10 milligram (mg) TabDrug
Also called Benazepril
Patients administered Benazepril by oral at a dose of 5mg or 10mg once a day at least 6 months.
| Study group | Role | What they receive |
|---|---|---|
| Hydroxychloroquine Cohort | Experimental | Patients in the cohort will receive Hydroxychloroquine(HCQ) throughout the study.Patients administered HCQ by oral at a dose of 6.5mg per kilogram twice a day for 6 months. During treatment with HCQ, patients also received enalapril(5-10mg qd). Receives: Drug: Hydroxychloroquine Sulfate 100 milligram (mg) Tab; Drug: Benazepril hydrochloride 10 milligram (mg) Tab |
| Comparator Cohort | Sham comparator | During treatment with HCQ, Patients randomized to Comparator Cohort only received enalapril(5-10mg qd). Receives: Drug: Benazepril hydrochloride 10 milligram (mg) Tab |
What is being measured
The primary outcome is the main question the study is designed to answer.
Change in urinary erythrocyte count(/HP)
To assess the change in urinary erythrocyte count(/HP) from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
Measured: Baseline to maximum 48 weeks
Secondary outcomes (6)
Change in 24-hour urinary protein quantity
To assess the change in 24-hour urinary protein quantity from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
Measured: Baseline to maximum 48 weeks
Change in urinary albumin characterization
To assess the change in urinary albumin characterization from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
Measured: Baseline to maximum 48 weeks
Change in urinary albumin to creatinine ratio
To assess the change in urinary albumin to creatinine ratio from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
Measured: Baseline to maximum 48 weeks
Change in urinary erythrocyte count(urinary sediment analyzer)
To assess the change in urinary erythrocyte count(urinary sediment analyzer) from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
Measured: Baseline to maximum 48 weeks
Change in eGFR from baseline
To assess the increase in eGFR from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
Measured: Baseline to maximum 48 weeks
Number of participants with treatment-related adverse events
Safety will be assessed by monitoring adverse events, physical examinations and clinical laboratory test through 48 weeks.
Measured: Baseline to maximum 48 weeks
Timeline
From the start of the study to its completion; the mark is today. Estimated dates are the sponsor’s plan.
- First posted24 Jun 2021
- Study start8 Sep 2021
- Primary completion31 Dec 2024
- Study completion31 Dec 2024
Resources
- Official record on ClinicalTrials.govThe registry entry this page is built from, with its full change history.
- Publications (5)Papers the sponsor has linked to this study.
- Other trials for Alport Syndrome, X-LinkedStudies of the same condition, open and under way.
- What the trial phases meanHow a treatment moves from first tests in people to approval.
More details
For doctors and researchers: how the study is designed, who runs it, and its registry IDs.
Study design
- Study type
- Interventional
- Phase
- Phase 2
- Primary purpose
- Treatment
- Allocation
- Randomised
- Intervention model
- Parallel groups
- Masking
- None (open label)
- Enrolment
- 50 participants (actual)
Sponsor and investigators
- Lead sponsor
- Shanghai Children's Hospital
- Sponsor type
- University, hospital or other
- Responsible party
- Sponsor
- Investigators
- Wen-yan Huang, PhD, Study director, Shanghai Children's Hospital
IDs, dates and publications
- ClinicalTrials.gov ID
- NCT04937907
- Sponsor's protocol ID
- 2021SPNR001
- Other IDs
- 2019YLYM06
- Acronym
- CHXLAS
- Status last verified
- Feb 2026
- First submitted
- 17 Jun 2021
- Last updated
- 2 Mar 2026
- Results posted
- No
- Data monitoring committee
- No
- FDA-regulated drug
- No
- FDA-regulated device
- No
- Individual data sharing
- No
Publications
Hertz JM, Thomassen M, Storey H, Flinter F. Clinical utility gene card for: Alport syndrome - update 2014. Eur J Hum Genet. 2015 Sep;23(9). doi: 10.1038/ejhg.2014.254. Epub 2014 Nov 12. No abstract available.
PubMed 25388007Daga S, Donati F, Capitani K, Croci S, Tita R, Giliberti A, Valentino F, Benetti E, Fallerini C, Niccheri F, Baldassarri M, Mencarelli MA, Frullanti E, Furini S, Conticello SG, Renieri A, Pinto AM. New frontiers to cure Alport syndrome: COL4A3 and COL4A5 gene editing in podocyte-lineage cells. Eur J Hum Genet. 2020 Apr;28(4):480-490. doi: 10.1038/s41431-019-0537-8. Epub 2019 Nov 21.
PubMed 31754267Schrezenmeier E, Dorner T. Mechanisms of action of hydroxychloroquine and chloroquine: implications for rheumatology. Nat Rev Rheumatol. 2020 Mar;16(3):155-166. doi: 10.1038/s41584-020-0372-x. Epub 2020 Feb 7.
PubMed 32034323Yang YZ, Chen P, Liu LJ, Cai QQ, Shi SF, Chen YQ, Lv JC, Zhang H. Comparison of the effects of hydroxychloroquine and corticosteroid treatment on proteinuria in IgA nephropathy: a case-control study. BMC Nephrol. 2019 Aug 5;20(1):297. doi: 10.1186/s12882-019-1488-6.
PubMed 31382914Liu LJ, Yang YZ, Shi SF, Bao YF, Yang C, Zhu SN, Sui GL, Chen YQ, Lv JC, Zhang H. Effects of Hydroxychloroquine on Proteinuria in IgA Nephropathy: A Randomized Controlled Trial. Am J Kidney Dis. 2019 Jul;74(1):15-22. doi: 10.1053/j.ajkd.2019.01.026. Epub 2019 Mar 25.
PubMed 30922594
Study at a glance
From the registry record, last updated by the sponsor on 2 Mar 2026. Recruitment status is as the sponsor reported it: confirm with the study team.
- Official title
- Efficacy and Safety of Hydroxychloroquine in Patients With X-linked Alport Syndrome in China (CHXLAS)
- ClinicalTrials.gov ID
- NCT04937907
- Acronym / sponsor ID
- CHXLAS / 2021SPNR001
- Conditions
- Alport Syndrome, X-Linked
- Keywords
- Alport Syndrome, Hydroxychloroquine, Treatment
- Phase
- Phase 2
- Study type
- Interventional
- Recruitment status
- Completed
- Enrolment
- 50 participants (actual)
- Lead sponsor
- Shanghai Children's HospitalUniversity, hospital or other
- Study start
- 8 Sep 2021 (actual)
- Primary completion
- 31 Dec 2024 (actual)
- Study completion
- 31 Dec 2024 (actual)
- First posted
- 24 Jun 2021 (actual)
- Results
- Not posted in the source record
Clinical summary
The research question as the sponsor registered it. This describes what the study plans to test, not what it found.
This Phase 2 randomized controlled trial will study the safety, tolerability, and efficacy of Hydroxychloroquine in qualified patients with Alport syndrome. The trial will be open-label, randomized, controlled and will enroll up to 50 patients.
Detailed description
This Phase 2 randomized controlled trial will study the safety, tolerability, and efficacy of Hydroxychloroquine in qualified patients with Alport syndrome. The trial will be open-label, randomized, controlled and will enroll up to 50 patients.
Patients in the Phase 2 cohort will be randomized 1:1 to either Hydroxychloroquine Cohort or Comparator Cohort.
All patients in the study will follow the same visit and assessment schedule. Following randomization on Day 1, patients will be scheduled to be assessed during treatment at Weeks 4, 12, and 24. Patients will not receive study drug during a 24-week withdrawal period between Weeks 25 and 48. Patients will also be scheduled to be assessed at an in person follow up visit at Week 36, and 48.
Study design
- Primary purpose
- Treatment
- Allocation
- Randomised
- Intervention model
- Parallel groups
- Masking
- None (open label)
- Number of arms
- 2
| Arm | Type | Receives |
|---|---|---|
| Hydroxychloroquine Cohort | Experimental | Drug: Hydroxychloroquine Sulfate 100 milligram (mg) Tab, Drug: Benazepril hydrochloride 10 milligram (mg) TabPatients in the cohort will receive Hydroxychloroquine(HCQ) throughout the study.Patients administered HCQ by oral at a dose of 6.5mg per kilogram twice a day for 6 months. During treatment with HCQ, patients also received enalapril(5-10mg qd). |
| Comparator Cohort | Sham comparator | Drug: Benazepril hydrochloride 10 milligram (mg) TabDuring treatment with HCQ, Patients randomized to Comparator Cohort only received enalapril(5-10mg qd). |
Who may qualify
- Ages
- 3 to 18 years
- Sex
- All
- Healthy volunteers
- Not accepted
- Age groups
- Child, Adult
Key inclusion criteria (7 listed)
- Male or female;
- Age 3-18 years old;
- Diagnosis of Alport syndrome by genetic testing (documented mutation in a gene associated with Alport syndrome, including COL4A3, COL4A4, or COL4A5) or histologic assessment using electron microscopy;
- Screening eGFR ≥ 90 mL/min/1.73 m2;
- ACE inhibitor and/or ARB, the dosing regimen should be stable for at least 4 weeks prior to screening;
Key exclusion criteria (7 listed)
- Causes of chronic kidney disease aside from Alport syndrome (including but not limited to other heritable disorders leading to chronic kidney disease, diabetic nephropathy, hypertensive nephropathy, lupus nephritis, IgA nephropathy);
- Prior exposure to hydroxychloroquine;
- Ongoing chronic hemodialysis or peritoneal dialysis therapy;
- Renal transplant recipient;
- Any clinically significant illness within 4 weeks before screening or surgical or medical condition (other than Alport syndrome) that could interfere with the subject's study compliance; confound the study results; impact subject safety; or significantly alter the absorption, distribution, metabolism, or excretion of drugs;
Eligibility is decided by the study team after screening; this overview does not establish that a patient qualifies. Full inclusion and exclusion criteria.
Interventions
| Intervention | Type | Arms |
|---|---|---|
| Hydroxychloroquine Sulfate 100 milligram (mg) TabAlso: HCQPatients administered HCQ by oral at a dose of 6.5mg per kilogram twice a day at least 6 months. | Drug | Hydroxychloroquine Cohort |
| Benazepril hydrochloride 10 milligram (mg) TabAlso: BenazeprilPatients administered Benazepril by oral at a dose of 5mg or 10mg once a day at least 6 months. | Drug | Comparator Cohort, Hydroxychloroquine Cohort |
Primary outcome
Change in urinary erythrocyte count(/HP)
Time frame: Baseline to maximum 48 weeks
To assess the change in urinary erythrocyte count(/HP) from baseline to week 48 for patients receiving active drug, compared to patients in Comparator Cohort.
6 secondary outcomes
Change in 24-hour urinary protein quantity
Time frame: Baseline to maximum 48 weeks
Change in urinary albumin characterization
Time frame: Baseline to maximum 48 weeks
Change in urinary albumin to creatinine ratio
Time frame: Baseline to maximum 48 weeks
Change in urinary erythrocyte count(urinary sediment analyzer)
Time frame: Baseline to maximum 48 weeks
Change in eGFR from baseline
Time frame: Baseline to maximum 48 weeks
Number of participants with treatment-related adverse events
Time frame: Baseline to maximum 48 weeks
Results and safety
The study is completed, but results are not available in the source record. That does not mean the treatment did or did not work.
Research links
- Official record on ClinicalTrials.govLast updated by the sponsor 2 Mar 2026.
- Background: PubMed 25388007Hertz JM, Thomassen M, Storey H, Flinter F. Clinical utility gene card for: Alport syndrome - update 2014. Eur J Hum Genet. 2015 Sep;23(9). doi: 10.1038/ejhg.2014.254. Epub 2014 Nov 12. No abstract available.
- Background: PubMed 31754267Daga S, Donati F, Capitani K, Croci S, Tita R, Giliberti A, Valentino F, Benetti E, Fallerini C, Niccheri F, Baldassarri M, Mencarelli MA, Frullanti E, Furini S, Conticello SG, Renieri A, Pinto AM. New frontiers to cure Alport syndrome: COL4A3 and COL4A5 gene editing in podocyte-lineage cells. Eur J Hum Genet. 2020 Apr;28(4):480-490. doi: 10.1038/s41431-019-0537-8. Epub 2019 Nov 21.
- Background: PubMed 32034323Schrezenmeier E, Dorner T. Mechanisms of action of hydroxychloroquine and chloroquine: implications for rheumatology. Nat Rev Rheumatol. 2020 Mar;16(3):155-166. doi: 10.1038/s41584-020-0372-x. Epub 2020 Feb 7.
- Background: PubMed 31382914Yang YZ, Chen P, Liu LJ, Cai QQ, Shi SF, Chen YQ, Lv JC, Zhang H. Comparison of the effects of hydroxychloroquine and corticosteroid treatment on proteinuria in IgA nephropathy: a case-control study. BMC Nephrol. 2019 Aug 5;20(1):297. doi: 10.1186/s12882-019-1488-6.
- Background: PubMed 30922594Liu LJ, Yang YZ, Shi SF, Bao YF, Yang C, Zhu SN, Sui GL, Chen YQ, Lv JC, Zhang H. Effects of Hydroxychloroquine on Proteinuria in IgA Nephropathy: A Randomized Controlled Trial. Am J Kidney Dis. 2019 Jul;74(1):15-22. doi: 10.1053/j.ajkd.2019.01.026. Epub 2019 Mar 25.
- Individual participant dataSharing planned: No
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Referral and contact
AzTrials does not enrol participants or take referrals. Contact the study team or a site listed below; they decide who can take part. This study is not recruiting at the moment.
Wen-yan Huang, PhD study director
Shanghai Children's Hospital
1 site in 1 country: see every site and its status.
Questions about this trial
What is this clinical trial studying?
A Phase 2 study testing Hydroxychloroquine Sulfate 100 milligram (mg) Tab and Benazepril hydrochloride 10 milligram (mg) Tab in people with Alport Syndrome, X-Linked, run by Shanghai Children's Hospital at 1 site in China.
The full registered description is in the About this study section and the official record.
Who may be eligible to take part?
The sponsor lists 7 inclusion and 7 exclusion criteria. Eligibility is decided by the study team after screening, so read the full criteria and contact a listed site.
Is this clinical trial currently recruiting?
The record says: finished, as of the sponsor's last update on 2 Mar 2026. Status can change between updates, so confirm with the study contact before making plans.
Where is the study taking place?
The record lists 1 site in China. Whether a site is taking part right now should be confirmed with that site. See every site.
What are the possible benefits and risks?
They depend on the study and the treatment, and no study can promise a benefit. Some participants in this study may receive a placebo. The study team explains the known risks during informed consent, before anyone joins; the record itself does not list them.
What does this phase mean?
Phase 2 studies give the treatment to a larger group to see whether it has the intended effect and to keep checking safety.
Not every study follows the same path, and some studies (observational studies, device studies) have no phase.
Are results available for this study?
The study is completed, but results are not available in the source record. That does not mean the treatment did or did not work.
How can a doctor refer a patient or contact the research team?
The record lists no contact. The official record names the sponsor, who can be asked directly. AzTrials does not enrol participants or take referrals.
What does the primary outcome measure?
Change in urinary erythrocyte count(/HP) (time frame: Baseline to maximum 48 weeks). It is what the study was designed to measure, not a finding.
Where can I read the original study information?
On the ClinicalTrials.gov record for NCT04937907, which also lists 5 linked publications.
Does a listing mean the treatment is approved or proven to work?
No. A listing means the study is registered. It does not show that the treatment is safe, works, or is approved by a regulator.
How often is this information updated?
AzTrials copies changed records from ClinicalTrials.gov every night and reloads the whole registry every week. The sponsor last updated this record on 2 Mar 2026.